PUBLICATION

Retinoic acid-dependent regulation of miR-19 expression elicits vertebrate axis defects

Authors
Franzosa, J.A., Bugel, S.M., Tal, T.L., La Du, J.K., Tilton, S.C., Waters, K.M., and Tanguay, R.L.
ID
ZDB-PUB-130904-42
Date
2013
Source
FASEB journal : official publication of the Federation of American Societies for Experimental Biology   27(12): 4866-76 (Journal)
Registered Authors
Tanguay, Robyn L., Tilton, Susan C.
Keywords
microRNAs, somitogenesis, zebrafish
Datasets
GEO:GSE49917
MeSH Terms
  • Animals
  • Body Patterning*
  • Cytochrome P-450 Enzyme System/metabolism
  • Gene Expression Regulation, Developmental*
  • MicroRNAs/genetics
  • MicroRNAs/metabolism*
  • Somites/drug effects
  • Somites/embryology
  • Somites/metabolism
  • Transcription, Genetic*
  • Tretinoin/metabolism*
  • Tretinoin/pharmacology
  • Zebrafish
PubMed
23975936 Full text @ FASEB J.
Abstract

Retinoic acid (RA) is involved in multifarious and complex functions necessary for vertebrate development. RA signaling is reliant on strict enzymatic regulation of RA synthesis and metabolism. Improper spatiotemporal expression of RA during development can result in vertebrate axis defects. microRNAs (miRNAs) are also pivotal in orchestrating developmental processes. While mechanistic links between miRNAs and axial development are established, the role of miRNAs in regulating metabolic enzymes responsible for RA abundance during axis formation has yet to be elucidated. Our results uncovered a role of miR-19 family members in controlling RA metabolism through the regulation of CYP26A1 during vertebrate axis formation. Global miRNA expression profiling showed that developmental RA exposure suppressed the expression of miR-19 family members during zebrafish somitogenesis. A reporter assay confirmed that cyp26a1 is a bona fide target of miR-19 in vivo. Transient knockdown of miR-19 phenocopied axis defects caused by RA exposure. Exogenous miR-19 rescued the axis defects induced by RA exposure. Taken together, these results indicate that the teratogenic effects of RA exposure result, in part, from repression of miR-19 expression and subsequent misregulation of cyp26a1. This highlights a previously unidentified role of miR-19 in facilitating vertebrate axis development via regulation of RA signaling.

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